Neurogenic involvement in a case of oculopharyngeal muscular dystrophy

Muscle Nerve. 2002 Jan;25(1):98-101. doi: 10.1002/mus.1213.

Abstract

We report the case of a 65-year-old man with a 15-year history of oculopharyngeal muscular dystrophy (OPMD) harboring a (GCG)11 mutation of the poly(A)-binding protein 2 (PABP2) gene. He developed, early in the course of the disease, a severe chronic axonal neuropathy. Although the primary myopathic origin of the disease appears to be established, a small number of cases of OPMD with neuropathic features have been described. This case raises the question of a possible neurogenic component to this disease and the role of the length of the mutation in phenotype severity.

Publication types

  • Case Reports

MeSH terms

  • Electromyography
  • Humans
  • Male
  • Middle Aged
  • Muscle, Skeletal / pathology
  • Muscle, Skeletal / physiopathology
  • Muscular Dystrophies / genetics
  • Muscular Dystrophies / pathology
  • Muscular Dystrophies / physiopathology*
  • Mutation
  • Peripheral Nerves / physiopathology*
  • Peroneal Nerve / pathology
  • Poly(A)-Binding Proteins
  • RNA-Binding Proteins / genetics

Substances

  • Poly(A)-Binding Proteins
  • RNA-Binding Proteins