Identification of a novel cathepsin C mutation (p.W185X) in a Brazilian kindred with Papillon-Lefèvre syndrome

Mol Genet Metab. 2002 Jun;76(2):145-7. doi: 10.1016/s1096-7192(02)00031-8.

Abstract

Papillon-Lefèvre syndrome (PLS) is an autosomal recessive palmoplantar keratoderma caused by cathepsin C (CTSC) gene mutations. This study reports CTSC mutational and enzyme analyses in a consanguineous Brazilian family with PLS, representing the first enzymatic analysis of a Brazilian kinship with PLS. This family segregates a novel PLS-related mutation, p.W185X, that is associated with a complete loss of enzymatic activity.

MeSH terms

  • Amino Acid Sequence
  • Amino Acid Substitution
  • Animals
  • Base Sequence
  • Brazil
  • Cathepsin C / genetics*
  • Consanguinity
  • Conserved Sequence
  • DNA / genetics
  • DNA Mutational Analysis
  • Female
  • Heterozygote
  • Homozygote
  • Humans
  • Male
  • Papillon-Lefevre Disease / genetics*
  • Pedigree
  • Point Mutation*
  • Sequence Homology, Amino Acid
  • Species Specificity

Substances

  • DNA
  • Cathepsin C