Novel mutation in the 5' splice site of exon 4 of the TCOF1 gene in the patient with Treacher Collins syndrome

Am J Med Genet A. 2003 Dec 1;123A(2):169-71. doi: 10.1002/ajmg.a.20312.

Abstract

Treacher Collins syndrome (TCS) is caused by mutations in the TCOF1 gene. This gene encodes a serine/alanine-rich protein called treacle. The structure of the entire TCOF1 gene was investigated in a patient with TCS. We detected a novel deletion (376delAAGGTGAGTGGGACTGCC) spanning 3 bp of exon 4 and 15 bp of the adjacent intronic sequence. This mutation causes premature termination of translation, resulting in a truncated protein devoid of nucleolar localization signal, and potential phosphorylation sites. Real-time PCR analysis showed different melting temperatures of the amplified fragment containing normal allele and that harboring the 18 bp deletion, thus providing a rapid screening assay for this and other deletions of the TCOF1 gene.

Publication types

  • Case Reports
  • Research Support, Non-U.S. Gov't

MeSH terms

  • Base Sequence
  • Exons
  • Humans
  • Male
  • Mandibulofacial Dysostosis / genetics*
  • Mutation / genetics*
  • Nuclear Proteins / genetics*
  • Pedigree
  • Phosphoproteins / genetics*
  • Polymorphism, Single-Stranded Conformational
  • Sequence Analysis, DNA
  • Sequence Deletion / genetics

Substances

  • Nuclear Proteins
  • Phosphoproteins
  • TCOF1 protein, human