Long CGG-repeat tracts are toxic to human cells: implications for carriers of Fragile X premutation alleles

FEBS Lett. 2005 May 9;579(12):2702-8. doi: 10.1016/j.febslet.2005.04.004. Epub 2005 Apr 18.

Abstract

People with 59-200 CGG.CCG-repeats in the 5' UTR of one of their FMR1 genes are at risk for Fragile X tremor and ataxia syndrome. Females are also at risk for premature ovarian failure. These symptoms are thought to be due to the presence of the repeats at the DNA and/or RNA level. We show here that long transcribed but untranslated CGG-repeat tracts are toxic to human cells and alter the expression of a wide variety of different genes including caspase-8, CYFIP, Neurotensin and UBE3A.

Publication types

  • Comparative Study

MeSH terms

  • 5' Untranslated Regions
  • Adaptor Proteins, Signal Transducing / genetics
  • Adaptor Proteins, Signal Transducing / metabolism
  • Alleles*
  • Annexin A5 / drug effects
  • Annexin A5 / metabolism
  • Ataxia / genetics
  • Blotting, Western
  • Caspase 8
  • Caspases / analysis
  • Caspases / genetics
  • Caspases / metabolism
  • Cell Line
  • Cell Survival
  • Culture Media, Serum-Free
  • Dose-Response Relationship, Drug
  • Doxycycline / pharmacology
  • Female
  • Fragile X Syndrome / genetics*
  • Gene Expression Profiling
  • Gene Expression Regulation
  • Herbicides / pharmacology
  • Heterozygote*
  • Humans
  • Mutation
  • Neurotensin / genetics
  • Neurotensin / metabolism
  • Oligonucleotide Array Sequence Analysis
  • Paraquat / pharmacology
  • Staurosporine / pharmacology
  • Trinucleotide Repeat Expansion / drug effects*
  • Trinucleotide Repeat Expansion / genetics
  • Ubiquitin-Protein Ligases / genetics
  • Ubiquitin-Protein Ligases / metabolism

Substances

  • 5' Untranslated Regions
  • Adaptor Proteins, Signal Transducing
  • Annexin A5
  • CYFIP1 protein, human
  • Culture Media, Serum-Free
  • Herbicides
  • Neurotensin
  • UBE3A protein, human
  • Ubiquitin-Protein Ligases
  • CASP8 protein, human
  • Caspase 8
  • Caspases
  • Staurosporine
  • Doxycycline
  • Paraquat