Molecular genetic analyses in neurofibromatosis type 1 patients with tumors

Cancer Genet Cytogenet. 2006 Mar;165(2):167-71. doi: 10.1016/j.cancergencyto.2005.08.029.

Abstract

Neurofibromatosis type 1 (NF1) is one of the most common autosomal dominant disorders. NF1 is clinically characterized by neurofibromas, pigmentation anomalies, and an increased risk of malignant tumors. The NF1 gene product, neurofibromin, has a GTPase-activating protein domain (GRD) that interacts with the Ras protein, which is crucial in regulating signal transduction and cell proliferation/differentiation. We performed mutation analyses in the NF1-GRD region (exons 21-27a) and in exons 4b, 16, 29, and 37, and intron 28 in 17 NF1 patients with tumors. We identified a large deletion in the NF1 gene in a patient with a rhabdomyosarcoma as well as a variation in intron 22 in a patient with an optic glioma. We also found a 4-base pair deletion in another patient with optic glioma. In addition, allelic loss of the NF1 locus was shown in a pilocytic astrocytoma. Functional analyses of mutations in the NF1 gene may provide further insights into the pathogenesis of NF1 tumors.

Publication types

  • Research Support, Non-U.S. Gov't

MeSH terms

  • Adolescent
  • Child
  • Child, Preschool
  • Exons
  • Female
  • Humans
  • Introns
  • Loss of Heterozygosity
  • Male
  • Middle Aged
  • Mutation
  • Neurofibromatosis 1 / genetics*
  • Polymerase Chain Reaction
  • Polymorphism, Single-Stranded Conformational