β-globin gene cluster haplotypes in a cohort of 221 children with sickle cell anemia or Sβ⁰-thalassemia and their association with clinical and hematological features

Acta Haematol. 2010;124(3):162-70. doi: 10.1159/000320271. Epub 2010 Oct 12.

Abstract

Background/aims: β(S)-Haplotype prevalence and its associations with clinical and hematological characteristics were assessed in Brazilian children with sickle cell anemia or Sβ⁰-thalassemia.

Methods: A retrospective randomized cohort study was undertaken with 208 SS and 13 Sβ⁰-thalassemia children derived from the Newborn Screening Program of the state of Minas Gerais. β(S)-Haplotypes were determined by PCR-RFLP.

Results: Thirty-nine percent of the SS subjects had the CAR/CAR genotype, 33% had CAR/Ben, 24% had Ben/Ben, 1% had CAR/Atp, 1% had Ben/Atp, and 1% had Arab-Indian/Ben; 1% could not be characterized. Of the Sβ⁰-thalassemia children, 5 were CAR/undefined, 2 were Ben/undefined, and 1 was CAM/undefined. There was no significant association between β(S)-haplotypes and the total Hb, Hb F, MCV, MCH, WBC, and reticulocyte count among the SS children. Likewise, no significant association was detected between β(S)-haplotypes and the frequency of acute chest syndrome episodes, blood transfusions, splenic sequestration, or cerebrovascular disease (high-risk/conditional transcranial Doppler ultrasonography or clinical stroke). A limited number of Sβ⁰-thalassemia children precluded valid analyses.

Conclusions: The prevalence of β(S)-haplotypes in this study is in agreement with the historical records of African slaves brought to the state of Minas Gerais. Furthermore, β(S)-haplotypes CAR and Ben were not associated with any analyzed feature of children with sickle cell anemia.

Publication types

  • Research Support, Non-U.S. Gov't

MeSH terms

  • Anemia, Sickle Cell / blood
  • Anemia, Sickle Cell / genetics*
  • Base Sequence
  • Brazil
  • Child
  • Child, Preschool
  • Cohort Studies
  • DNA Primers / genetics
  • Female
  • Gene Frequency
  • Haplotypes
  • Hemoglobin, Sickle / genetics*
  • Humans
  • Infant
  • Male
  • Multigene Family
  • Retrospective Studies
  • beta-Globins / genetics*
  • beta-Thalassemia / blood
  • beta-Thalassemia / genetics*

Substances

  • DNA Primers
  • Hemoglobin, Sickle
  • beta-Globins