Camurati-Engelmann disease with obesity in a newly identified family carrying a missense p.Arg156Cys mutation in the TGFB1 gene

Am J Med Genet A. 2013 Aug;161A(8):2074-7. doi: 10.1002/ajmg.a.36022. Epub 2013 Jul 3.

Abstract

We report on a family affected by Camurati-Engelmann disease, characterized by radiological signs limited to the tibia, and associated with overweight or obesity, which is not a known feature of this disorder. The affected patients were heterozygous for a c.466C > T mutation (which predicts p.Arg156Cys) in the latency associated protein (LAP)-coding domain of the TGFB1 gene. This mutation had previously been reported once in another family with a similar, atypical phenotype, which suggests a possible phenotype/genotype relationship.

Keywords: Camurati-Engelman; TGFB1; mutation; obesity.

MeSH terms

  • Adult
  • Camurati-Engelmann Syndrome / complications
  • Camurati-Engelmann Syndrome / diagnosis
  • Camurati-Engelmann Syndrome / genetics*
  • Child
  • Female
  • Heterozygote
  • Humans
  • Male
  • Middle Aged
  • Mutation, Missense / genetics*
  • Obesity / complications
  • Obesity / diagnosis
  • Obesity / genetics*
  • Pedigree
  • Phenotype
  • Transforming Growth Factor beta1 / genetics*
  • Young Adult

Substances

  • TGFB1 protein, human
  • Transforming Growth Factor beta1