Complexity of the alpha-globin genotypes identified with thalassemia screening in Sardinia

Blood Cells Mol Dis. 2014 Jan;52(1):46-9. doi: 10.1016/j.bcmd.2013.06.004. Epub 2013 Jul 27.

Abstract

α-Thalassemia commonly results from deletions or point mutations in one or both α-globin genes located on chromosome 16p13.3 giving rise to complex and variable genotypes and phenotypes. Rarely, unusual non-deletion defects or atypical deletions down-regulate the expression of the α-globin gene. In the last decade of the program for β-thalassemia carrier screening and genetic counseling in Sardinia, the association of new techniques of molecular biology such as gene sequencing and Multiplex Ligation-dependent Probe Amplification (MLPA) to conventional methods has allowed to better define several thalassemic genotypes and the complex variability of the α-cluster with its flanking regions, with a high frequency of different genotypes and compound heterozygosity for two α mutations even in the same family. The exact molecular definition of the genotypes resulting from the interactions among the large number of α-thalassemia determinants and with β-thalassemia, is important for a correct correlation of genotype-phenotype and to prevent underdiagnosis of carrier status which could hamper the effectiveness of a screening program particularly in those regions where a high frequency of hemoglobinopathies is present.

Keywords: Additional alpha globin genes; Alpha thalassemia; Compound heterozygosity; Hb-variants.

MeSH terms

  • Alleles
  • Carrier State
  • Chromosomes, Human, Pair 16
  • Gene Frequency
  • Genetic Association Studies
  • Genetic Testing
  • Genotype*
  • Heterozygote
  • Humans
  • Italy
  • Mutation*
  • Phenotype
  • Polymorphism, Genetic*
  • Severity of Illness Index
  • alpha-Globins / genetics*
  • alpha-Thalassemia / diagnosis
  • alpha-Thalassemia / genetics*
  • beta-Thalassemia / diagnosis
  • beta-Thalassemia / genetics*

Substances

  • alpha-Globins