Prenatal molecular diagnosis of X-linked hydrocephalus via a silent C924T mutation in the L1CAM gene

Congenit Anom (Kyoto). 2014 Nov;54(4):243-5. doi: 10.1111/cga.12069.

Abstract

We present a case of a patient whose L1CAM gene in X-chromosome has a C924T transition. Her first son's ventriculomegaly was prenatally detected. A mature infant was born, his head circumference was large, and thumbs were bilaterally adducted. X-linked hydrocephalus (XLH) was suspected. The DNA examination revealed that both her and boy's LICAM gene had a C924T transition. She became pregnant 5 years later and amniocentesis was performed. The results of cytogenetic analysis revealed that the fetus was female. She continued her pregnancy and delivered a healthy girl. She again became pregnant 3 years later. The chromosomal analysis revealed that the fetus was male. Fetal DNA analysis determined that the fetus had the inherited mutation. She chose to terminate the pregnancy. A C924T mutation can be disease causing for XLH, and the detection of this mutation would aid in genetic counseling for the prenatal diagnosis of XLH.

Keywords: L1CAM gene; X-linked hydrocephalus; prenatal diagnosis; silent mutation.

Publication types

  • Case Reports

MeSH terms

  • Adult
  • Cerebral Aqueduct / abnormalities*
  • Female
  • Genetic Diseases, X-Linked / diagnosis*
  • Genetic Diseases, X-Linked / genetics
  • Humans
  • Hydrocephalus / diagnosis*
  • Hydrocephalus / genetics
  • Infant
  • Male
  • Mutation
  • Neural Cell Adhesion Molecule L1 / genetics*
  • Pathology, Molecular
  • Pedigree
  • Pregnancy
  • Prenatal Diagnosis*

Substances

  • Neural Cell Adhesion Molecule L1

Supplementary concepts

  • Hydrocephalus, X-linked