DICER1/Alu RNA dysmetabolism induces Caspase-8-mediated cell death in age-related macular degeneration

Proc Natl Acad Sci U S A. 2014 Nov 11;111(45):16082-7. doi: 10.1073/pnas.1403814111. Epub 2014 Oct 27.

Abstract

Geographic atrophy, an advanced form of age-related macular degeneration (AMD) characterized by death of the retinal pigmented epithelium (RPE), causes untreatable blindness in millions worldwide. The RPE of human eyes with geographic atrophy accumulates toxic Alu RNA in response to a deficit in the enzyme DICER1, which in turn leads to activation of the NLRP3 inflammasome and elaboration of IL-18. Despite these recent insights, it is still unclear how RPE cells die during the course of the disease. In this study, we implicate the involvement of Caspase-8 as a critical mediator of RPE degeneration. Here we show that DICER1 deficiency, Alu RNA accumulation, and IL-18 up-regulation lead to RPE cell death via activation of Caspase-8 through a Fas ligand-dependent mechanism. Coupled with our observation of increased Caspase-8 expression in the RPE of human eyes with geographic atrophy, our findings provide a rationale for targeting this apoptotic pathway in this disease.

Keywords: caspase; inflammasome; macular degeneration.

Publication types

  • Research Support, N.I.H., Extramural
  • Research Support, Non-U.S. Gov't
  • Research Support, U.S. Gov't, Non-P.H.S.

MeSH terms

  • Alu Elements*
  • Animals
  • Apoptosis*
  • Caspase 8 / genetics
  • Caspase 8 / metabolism*
  • DEAD-box RNA Helicases / genetics
  • DEAD-box RNA Helicases / metabolism*
  • Eye Proteins / genetics
  • Eye Proteins / metabolism*
  • Humans
  • Interleukin-18 / genetics
  • Interleukin-18 / metabolism
  • Macular Degeneration / metabolism*
  • Macular Degeneration / pathology
  • Mice
  • Mice, Knockout
  • RNA / genetics
  • RNA / metabolism*
  • Ribonuclease III / genetics
  • Ribonuclease III / metabolism*
  • Up-Regulation / genetics

Substances

  • Eye Proteins
  • Interleukin-18
  • RNA
  • DICER1 protein, human
  • Dicer1 protein, mouse
  • Ribonuclease III
  • CASP8 protein, human
  • Casp8 protein, mouse
  • Caspase 8
  • DEAD-box RNA Helicases