An unusual case of schwannomatosis with bilateral maxillary sinus schwannomas and a novel SMARCB1 gene mutation

J Neurosurg Spine. 2016 Jan;24(1):160-6. doi: 10.3171/2015.4.SPINE15192. Epub 2015 Oct 2.

Abstract

Schwannomas are benign tumors that arise from Schwann cells in the peripheral nervous system. Patients with multiple schwannomas without signs and symptoms of neurofibromatosis Type 1 or 2 have the rare disease schwannomatosis. Tumors in these patients occur along peripheral nerves throughout the body. Mutations of the SMARCB1 gene have been described as one of the predisposing genetic factors in the development of this disease. This report describes a patient who was observed for 6 years after having undergone removal of 7 schwannomas, including bilateral maxillary sinus schwannomas, a tumor that has not been previously reported. Genetic analysis revealed a novel mutation of c.93G>A in exon 1 of the SMARCB1 gene.

Keywords: SMARCB1; oncology; perinasal schwannoma; peripheral nerve sheath tumor; schwannomatosis.

Publication types

  • Case Reports

MeSH terms

  • Chromosomal Proteins, Non-Histone / genetics*
  • DNA-Binding Proteins / genetics*
  • Exons
  • Female
  • Genetic Predisposition to Disease
  • Humans
  • Maxillary Sinus / pathology*
  • Mutation / genetics*
  • Neurilemmoma / diagnosis
  • Neurilemmoma / genetics*
  • Neurilemmoma / pathology
  • Neurofibromatoses / diagnosis
  • Neurofibromatoses / genetics*
  • Neurofibromatoses / pathology
  • SMARCB1 Protein
  • Skin Neoplasms / diagnosis
  • Skin Neoplasms / genetics*
  • Skin Neoplasms / pathology
  • Transcription Factors / genetics*
  • Young Adult

Substances

  • Chromosomal Proteins, Non-Histone
  • DNA-Binding Proteins
  • SMARCB1 Protein
  • SMARCB1 protein, human
  • Transcription Factors

Supplementary concepts

  • Schwannomatosis