Exome sequencing reveals a novel nonsense mutation of GLI3 in a Chinese family with 'non-syndromic' pre-axial polydactyly

J Hum Genet. 2016 Oct;61(10):907-910. doi: 10.1038/jhg.2016.76. Epub 2016 Jun 16.

Abstract

Polydactyly is a clinically and genetically heterogeneous disorder. In the current report, we present a five-generation Chinese family with non-syndromic pre-axial polydactyly with thumb polydactyly (pre-axial polydactyly type I (PPD-I)) as a major clinical feature. Using whole-exome sequencing (WES), a novel nonsense mutation c.714T>A (p.Y238*) of the glioma-associated oncogene family zinc-finger 3 gene (GLI3) was identified as the pathogenic mutation for this family. Our study has, for the first time, suggested the possible contribution of GLI3 in the patheogenesis of PPD-I, and demonstrated that WES provided an applicable diagnostic tool for identifying mutations in disorders with highly genetical heterogeneity such as polydactyly.

MeSH terms

  • China
  • Codon, Nonsense*
  • Computational Biology / methods
  • DNA Mutational Analysis
  • Exome
  • Female
  • High-Throughput Nucleotide Sequencing
  • Humans
  • Kruppel-Like Transcription Factors / genetics*
  • Male
  • Nerve Tissue Proteins / genetics*
  • Pedigree
  • Phenotype
  • Polydactyly / diagnosis*
  • Polydactyly / genetics*
  • Thumb / abnormalities*
  • Zinc Finger Protein Gli3

Substances

  • Codon, Nonsense
  • GLI3 protein, human
  • Kruppel-Like Transcription Factors
  • Nerve Tissue Proteins
  • Zinc Finger Protein Gli3

Supplementary concepts

  • Polydactyly preaxial type 1