Bilateral Piriform sinus fistulas: a case study and review of management options

J Otolaryngol Head Neck Surg. 2018 Feb 14;47(1):16. doi: 10.1186/s40463-018-0258-y.

Abstract

Background: Piriform sinus fistulas occur due to developmental abnormalities of the third and fourth branchial arches, and almost always occur unilaterally. They generally present as recurrent abscesses in the anterior-inferior neck, with concurrent thyroiditis. They have conventionally been managed with complete removal of the sinus tract, and thyroidectomy if required; however, endoscopic approaches have been increasingly favored. Herein we describe a case of bilateral piriform sinus fistulas, and present a review of the literature concerning their endoscopic management.

Case presentation: Our patient was determined to have bilateral piriform sinus fistulas based on computer tomography, magnetic resonance imaging and microlaryngoscopy. We performed electrocauterization of the proximal fistula tracts, followed by injection of fibrin sealent. Our patient has not had a recurrence in the ten months since his procedure. There were no complications. Twenty-three articles describing an endoscopic approach to these fistulas were identified through PubMed, and a search through the references of related articles was completed.

Conclusion: Of one hundred and ninety-five patient cases we reviewed, an endoscopic procedure success rate of 82% and complication rate of 5.6% was determined. Piriform sinus fistulas that occur bilaterally are a rare congenital abnormality of the neck. Endoscopic approaches are an acceptable alternative option to open procedures, with similar success and a lower rate of complications.

Keywords: Branchial arch abnormality; Endoscopic repair; Fourth Branchial fistula; Piriform sinus fistula; Suppurative Thyroiditis; Third Branchial fistula.

Publication types

  • Case Reports
  • Review

MeSH terms

  • Female
  • Follow-Up Studies
  • Humans
  • Laryngoscopy / methods*
  • Laser Therapy / methods*
  • Magnetic Resonance Imaging / methods
  • Male
  • Multimodal Imaging / methods*
  • Predictive Value of Tests
  • Pyriform Sinus / abnormalities*
  • Pyriform Sinus / diagnostic imaging
  • Pyriform Sinus / surgery*
  • Respiratory Tract Fistula / diagnostic imaging
  • Respiratory Tract Fistula / surgery*
  • Risk Assessment
  • Tomography, X-Ray Computed / methods
  • Treatment Outcome