HIST1H1E syndrome with type 2 diabetes

BMJ Case Rep. 2021 Jul 21;14(7):e241907. doi: 10.1136/bcr-2021-241907.

Abstract

A 20-year-old woman was referred to the diabetes clinic with type 2 diabetes diagnosed at the age of 19. Her body mass index was 31.4 kg/m2, HbA1C was 76 mmol/mol, GAD antibodies were negative with a detectable C-peptide. She had a characteristic facial appearance with widespread eyes, posterior hairline suggesting a facial gestalt and abnormal dentition. She also had hypothyroidism, mild intellectual disability, primary amenorrhoea and patent ductus arteriosus. Karyotyping reported normal 46XX karyotype. Genetic testing revealed a pathogenic variant in the gene encoding the HIST1H1E protein which confirmed her diagnosis of HIST1H1E syndrome. Type 2 diabetes has not been reported in previous cases of HIST1H1E and so this is the first reported case of type 2 diabetes with HIST1H1E syndrome.

Keywords: diabetes; disability; genetics; metabolic disorders; neuroendocrinology.

Publication types

  • Case Reports

MeSH terms

  • Adult
  • C-Peptide
  • Diabetes Mellitus, Type 2* / complications
  • Facies
  • Female
  • Histones
  • Humans
  • Intellectual Disability*
  • Young Adult

Substances

  • C-Peptide
  • Histones