A Novel Forkhead Box L2 Missense Mutation, c.1068G>C, in a Chinese Family With Blepharophimosis/Ptosis/ Epicanthus Inversus Syndrome

J Craniofac Surg. 2022 May 1;33(3):e238-e240. doi: 10.1097/SCS.0000000000008042. Epub 2021 Aug 9.

Abstract

The aim of the study was to report a novel forkhead box L2 (FOXL2) missense mutation in a Chinese blepharophimosis/ ptosis/epicanthus inversus syndrome family. Three generations of the Chinese family with blepharophimosis/ptosis/epicanthus inversus syndrome were enrolled in this study. Blood samples from patients of this family were collected and then analyzed by whole-exome sequencing. Confocal microscopy was performed to detect the subcellular location of FOXL2. Transactivation studies were performed and verified with real time polymerase chain reaction. A novel mutation (c.1068G>C) located in the downstream of deoxyribonucleic acid-binding forkhead domain was identified. Confocal photos showed the novel mutation did not disturb FOXL2 function, and the mutant protein could still transactivate steroidogenic acute regulatory protein, a key regulator of primary ovarian failure (POF). Our study revealed a novel missense mutation (c.1068G>C) and expanded the spectrum of FOXL2 gene mutations.

MeSH terms

  • Blepharophimosis* / diagnosis
  • Blepharophimosis* / genetics
  • China
  • Forkhead Box Protein L2* / genetics
  • Humans
  • Mutation, Missense
  • Pedigree
  • Skin Abnormalities* / diagnosis
  • Skin Abnormalities* / genetics
  • Urogenital Abnormalities* / diagnosis
  • Urogenital Abnormalities* / genetics

Substances

  • FOXL2 protein, human
  • Forkhead Box Protein L2

Supplementary concepts

  • Blepharophimosis, Ptosis, and Epicanthus Inversus