Analysis of uroporphyrinogen decarboxylase complementary DNAs in sporadic porphyria cutanea tarda

Gastroenterology. 1993 Jul;105(1):165-9. doi: 10.1016/0016-5085(93)90022-5.

Abstract

Background: Sporadic porphyria cutanea tarda (S-PCT) has been considered an acquired disease because of the generation of liver-specific inhibitors of uroporphyrinogen decarboxylase (URO-D) activity. Several families have been described with S-PCT in multiple generations, raising the possibility of an inherited basis for the disease. To determine if S-PCT is associated with mutant URO-Ds that might be sensitive to liver-specific inhibitors, a molecular analysis of genomic and hepatocellular URO-Ds was undertaken.

Methods: Total RNA from lymphoid cell lines from three unrelated patients with S-PCT and poly A+ RNA from liver biopsy samples from two additional patients was used as a template for single-stranded cDNA synthesis, and URO-D sequences were amplified and sequenced. DNA prepared from peripheral blood leukocytes was used as a template to polymerase chain reaction (PCR) amplify the promoter region of the URO-D gene. Sequencing of PCR products was performed completely in both directions by the chain termination method using a variety of custom oligonucleotide primers.

Results: Ten URO-D alleles were sequenced, and no mutations were found. The promoter region of the URO-D gene was also normal.

Conclusions: It is concluded that S-PCT is not due to mutations at the URO-D locus. If inherited factors are involved, other loci must be affected.

Publication types

  • Research Support, U.S. Gov't, P.H.S.

MeSH terms

  • Adult
  • Aged
  • Base Sequence
  • DNA / chemistry
  • DNA / genetics*
  • Female
  • Humans
  • Liver / enzymology
  • Male
  • Middle Aged
  • Molecular Sequence Data
  • Mutation
  • Porphyria Cutanea Tarda / enzymology*
  • Porphyria Cutanea Tarda / genetics
  • Uroporphyrinogen Decarboxylase / genetics*
  • Uroporphyrinogen Decarboxylase / metabolism

Substances

  • DNA
  • Uroporphyrinogen Decarboxylase