Treatment with rhG-CSF for osteomyelitis in a patient with p47-phox-deficient chronic granulomatous disease

Ann Hematol. 1997 Nov-Dec;75(5-6):243-6. doi: 10.1007/s002770050351.

Abstract

A 24-year-old woman with osteomyelitis was diagnosed as having p47-phox-deficient chronic granulomatous disease (CGD). The patient showed a marked deficiency of p47-phox, which is very rare in Japan. As the clinical response to various antibiotics including sulfamethoxazole-trimethoprim was not satisfactory, we added recombinant human granulocyte colony-stimulating factor (rhG-CSF) to the treatment protocol. We report the beneficial clinical course of the patient, together with the effect of rhG-CSF on the granulocyte function, and the present report indicates that rhG-CSF is useful for the treatment of antibiotic-resistant infection in the variant type of p47-phox-defective CGD.

Publication types

  • Case Reports

MeSH terms

  • Adult
  • Female
  • Granulocyte Colony-Stimulating Factor / therapeutic use*
  • Granulomatous Disease, Chronic / complications*
  • Granulomatous Disease, Chronic / genetics
  • Granulomatous Disease, Chronic / metabolism
  • Humans
  • NADPH Oxidases
  • Osteomyelitis / complications*
  • Osteomyelitis / drug therapy*
  • Phosphoproteins / deficiency*
  • Phosphoproteins / genetics
  • Recombinant Proteins / therapeutic use

Substances

  • Phosphoproteins
  • Recombinant Proteins
  • Granulocyte Colony-Stimulating Factor
  • NADPH Oxidases
  • neutrophil cytosolic factor 1